Rare Exome Sequence Variants in CLCN6 Reduce Blood Pressure Levels and Hypertension Risk.

نویسندگان

  • Bing Yu
  • Sara L Pulit
  • Shih-Jen Hwang
  • Jennifer A Brody
  • Najaf Amin
  • Paul L Auer
  • Joshua C Bis
  • Eric Boerwinkle
  • Gregory L Burke
  • Aravinda Chakravarti
  • Adolfo Correa
  • Albert W Dreisbach
  • Oscar H Franco
  • Georg B Ehret
  • Nora Franceschini
  • Albert Hofman
  • Dan-Yu Lin
  • Ginger A Metcalf
  • Solomon K Musani
  • Donna Muzny
  • Walter Palmas
  • Leslie Raffel
  • Alex Reiner
  • Ken Rice
  • Jerome I Rotter
  • Narayanan Veeraraghavan
  • Ervin Fox
  • Xiuqing Guo
  • Kari E North
  • Richard A Gibbs
  • Cornelia M van Duijn
  • Bruce M Psaty
  • Daniel Levy
  • Christopher Newton-Cheh
  • Alanna C Morrison
چکیده

BACKGROUND Rare genetic variants influence blood pressure (BP). METHODS AND RESULTS Whole-exome sequencing was performed on DNA samples from 17 956 individuals of European ancestry and African ancestry (14 497, first-stage discovery and 3459, second-stage discovery) to examine the effect of rare variants on hypertension and 4 BP traits: systolic BP, diastolic BP, pulse pressure, and mean arterial pressure. Tests of ≈170 000 common variants (minor allele frequency, ≥1%; statistical significance, P≤2.9×10(-7)) and gene-based tests of rare variants (minor allele frequency, <1%; ≈17 000 genes; statistical significance, P≤1.5×10(-6)) were evaluated for each trait and ancestry, followed by multiethnic meta-analyses. In the first-stage discovery, rare coding variants (splicing, stop-gain, stop-loss, nonsynonymous variants, or indels) in CLCN6 were associated with lower diastolic BP (cumulative minor allele frequency, 1.3%; β=-3.20; P=4.1×10(-6)) and were independent of a nearby common variant (rs17367504) previously associated with BP. CLCN6 rare variants were also associated with lower systolic BP (β=-4.11; P=2.8×10(-4)), mean arterial pressure (β=-3.50; P=8.9×10(-6)), and reduced hypertension risk (odds ratio, 0.72; P=0.017). Meta-analysis of the 2-stage discovery samples showed that CLCN6 was associated with lower diastolic BP at exome-wide significance (cumulative minor allele frequency, 1.1%; β=-3.30; P=5.0×10(-7)). CONCLUSIONS These findings implicate the effect of rare coding variants in CLCN6 in BP variation and offer new insights into BP regulation.

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عنوان ژورنال:
  • Circulation. Cardiovascular genetics

دوره 9 1  شماره 

صفحات  -

تاریخ انتشار 2016